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A326E

Category 3/4 — Most DruggableLikely pathogenicTransmembrane · predictedEditorial
AlanineGlutamate at position 326 · TM1 (314-334), helical transmembrane · WFS1 (Wolframin)

Alanine → Glutamate at position 326 inside TM1. ClinVar Likely pathogenic, DFNA6 hearing loss. AlphaMissense 0.940, DynaMut2 ΔΔG -0.33 kcal/mol (destabilising). Charge-introduction variant in TM1.

Interactive 3D Structure

Wild-type reference
Wild-type A326 — hydrogen bond to H322
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DynaMut2 mutant · A326E
Mutant E326 — hydrogen bond contact to H323 lost
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Bond changes · DynaMut2 interaction analysis

1 lost0 gained10 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondH322H322Preserved
Hydrogen bondH323Lost
Hydrogen bondF329F329Preserved
Hydrogen bondF330F330Preserved
Polar contactH322H322Preserved
Polar contactH323H323Preserved
Polar contactI324I324Preserved
Polar contactF329F329Preserved
Polar contactF330F330Preserved
Van der WaalsI324I324Preserved
HydrophobicF330F330Preserved

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.33kcal/mol
Destabilising — mild
AlphaMissense
0.940
LPath
AlphaFold pLDDT
77
model confidence
Schema
Cat 3/4
Category 3/4 — Most Druggable
ΔΔG confidence: Reduced confidence · Transmembrane
  • transmembrane position; predictor benchmarked on soluble proteins

This variant sits in the transmembrane band. The stability value was computed with a predictor benchmarked on water-soluble proteins. Published benchmarks of ddG predictors on membrane proteins report correlation below 0.4. Treat the magnitude as unreliable and the sign as weak evidence only.

Do not rank this value against a variant from a different region on ΔΔG alone.

Clinical Evidence

ClinVar classificationLikely pathogenic
Review statuscriteria provided, single submitter
Associated conditionsAutosomal dominant nonsyndromic hearing loss 6 (DFNA6)
InheritanceDFNA6 hearing loss documented.
Population frequency (gnomAD v4)Absent from gnomAD v4
cDNA changec.977C>A
ClinVar accessionVCV004687962
Last evaluated2025/08/25 00:00

Not observed in ~730k individuals — consistent with a rare allele (ACMG PM2_supporting).

Classified for1★ unverified submission

ClinVar classifies this variant as Likely pathogenic for Nonsyndromic hearing loss (DFNA6/14/38) (autosomal dominant, OMIM 600965). These are dominant WFS1-related disorders and are clinically distinct from classic recessive Wolfram syndrome. This classification is not a statement about Wolfram syndrome severity.

  • Nonsyndromic hearing loss (DFNA6/14/38)autosomal dominant · OMIM 600965submitted as: Autosomal dominant nonsyndromic hearing loss 6
  • This rests on a single submitter (1★). Treat the conditions above as submitted, not as documented phenotypes.
  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ single submitter. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
Absent from gnomAD v4
Homozygotes
Not available

No population breakdown — the variant is absent from gnomAD v4, so no ancestry group has an observed frequency.

No homozygotes — the variant is absent from gnomAD v4 altogether.

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position 326 sits in TM1. The AlphaFold model places A326 within 5 Å of ASN325 (2.5 Å), LEU327 (2.5 Å), HIS322 (3.6 Å), HIS323 (3.7 Å — partner of H323R Atlas card), and PHE329 (4.2 Å). The local environment includes two adjacent histidines (H322, H323).

Replacing alanine with glutamate introduces a negative charge into the bilayer-embedded TM1 environment. The carboxylate can interact with the nearby H322/H323 imidazoles when they're protonated, potentially forming a stable salt-bridge that differs from the wild-type fold geometry. But this rearrangement comes at a structural cost.

The |ΔΔG| of 0.33 reflects fold accommodation. AlphaMissense's 0.940 + DFNA6 confirm severe functional consequence. Mechanism is charge introduction at the TM1 H322-H323 cluster.

Amino-acid chemistry
Alanine (A) → Glutamate (E) — small methyl-bearing hydrophobic replaced by negatively-charged carboxylate-bearing residue.
Position in the protein
TM1 (residues 314–334) · position 326 mid-helix, bilayer-embedded (pLDDT 77).

Druggability Assessment

Category 3/4 — Most Druggable. |ΔΔG| = 0.33 — fold survives. AlphaMissense 0.940 + DFNA6 confirm severe functional consequence.

Mechanism is charge introduction into the TM1 H322-H323 cluster. Therapeutic strategy: site-directed at TM1 mid-helix.

Why this matters

A326E joins the TM1 variant cluster (W314R, H313Y, H323R, T321R, T321P, A326E). Six variants in or near TM1 in the Atlas — the helix is a recurring therapeutic target region.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the A326E PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download A326E PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Transmembrane314334 · Helical
Natural variant326326 · in dbSNP:rs369795224