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A342T

Category 4 — Stable Fold, Function DisruptedConflictingTransmembrane · predictedEditorial
AlanineThreonine at position 342 · TM2 (340-360), helical transmembrane · WFS1 (Wolframin)

Alanine → Threonine at position 342 inside TM2. ClinVar Conflicting including WFS1 spectrum + Wolfram. AlphaMissense 0.13 (below threshold) — AM under-call. DynaMut2 ΔΔG -0.72.

Interactive 3D Structure

Wild-type reference
Wild-type A342 — hydrogen bond to I338
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DynaMut2 mutant · A342T
Mutant T342 — van der waals contact to P346 lost
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Bond changes · DynaMut2 interaction analysis

1 lost6 gained6 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondI338I338Preserved
Hydrogen bondD339D339Preserved
Hydrogen bondW867Gained
Polar contactI338I338Preserved
Polar contactD339D339Preserved
Polar contactF340Gained
Polar contactP346P346Preserved
Polar contactW867Gained
Van der WaalsD339Gained
Van der WaalsF340Gained
Van der WaalsP346Lost
Van der WaalsW867Gained
HydrophobicW867W867Preserved

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.72kcal/mol
Destabilising — mild
AlphaMissense
0.131
LBen
AlphaFold pLDDT
73
model confidence
Schema
Cat 4
Category 4 — Stable Fold, Function Disrupted
ΔΔG confidence: Reduced confidence · Transmembrane
  • transmembrane position; predictor benchmarked on soluble proteins

This variant sits in the transmembrane band. The stability value was computed with a predictor benchmarked on water-soluble proteins. Published benchmarks of ddG predictors on membrane proteins report correlation below 0.4. Treat the magnitude as unreliable and the sign as weak evidence only.

Do not rank this value against a variant from a different region on ΔΔG alone.

Clinical Evidence

ClinVar classificationConflicting classifications of pathogenicity
Review statuscriteria provided, conflicting classifications
Associated conditionsWFS1-Related Spectrum Disorders; Wolfram syndrome 1
InheritanceMulti-phenotype.
Population frequency (gnomAD v4)Low frequency · AF 0.020%
cDNA changec.1024G>A
ClinVar accessionVCV000130747
Last evaluated2024/08/28 00:00

Observed in the general population.

Classified for1★ unverified submission

ClinVar classifies this variant as Conflicting classifications of pathogenicity for WFS1-related spectrum (unresolved mode) (dominant or recessive); Wolfram syndrome (classic) (autosomal recessive, OMIM 222300); Nonsyndromic hearing loss (DFNA6/14/38) (autosomal dominant, OMIM 600965); WFS1-related diabetes (autosomal dominant); Cataract 41 (autosomal dominant, OMIM 116400); Wolfram-like syndrome (autosomal dominant, OMIM 614296). ClinVar records this under a WFS1-spectrum label that spans both disease families — recessive Wolfram syndrome (biallelic) and the dominant WFS1-related disorders. The label does not resolve which applies, and it is not a severity statement.

  • WFS1-related spectrum (unresolved mode)dominant or recessivesubmitted as: WFS1-Related Spectrum Disorders
  • Wolfram syndrome (classic)autosomal recessive · OMIM 222300submitted as: Wolfram syndrome 1; Wolfram syndrome 1
  • Nonsyndromic hearing loss (DFNA6/14/38)autosomal dominant · OMIM 600965submitted as: Autosomal dominant nonsyndromic hearing loss 6; Autosomal dominant nonsyndromic hearing loss 6
  • WFS1-related diabetesautosomal dominantsubmitted as: Type 2 diabetes mellitus
  • Cataract 41autosomal dominant · OMIM 116400submitted as: Cataract 41
  • Wolfram-like syndromeautosomal dominant · OMIM 614296submitted as: Wolfram-like syndrome
  • Submitters conflict on this classification (1★). Treat the conditions above as submitted, not as documented phenotypes.
  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ conflicting classifications. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
AF 0.020% · 330 / 1,613,824 alleles
Homozygotes
1
Highest-frequency population
Middle Eastern · AF 0.050%

Highest in Middle Eastern: AF 0.050% (3 of 6,058 alleles), 2.4x the global figure. The global AF describes the general population, not the at-risk group.

1 homozygote reported in gnomAD v4 (1 South Asian). gnomAD excludes individuals with severe pediatric disease, so homozygotes in this dataset argue against a fully penetrant severe recessive phenotype and belong in the clinical picture. This is interpretive signal, not a classification.

Ancestry groupAllele freq.AC / ANHom.Carrier est.
Middle Eastern0.050%3 / 6,0580~1 in 1010
South Asian0.046%42 / 91,0561~1 in 1080
East Asian0.029%13 / 44,8600~1 in 1730
European (non-Finnish)0.021%248 / 1,179,8820~1 in 2380
Remaining individuals0.014%9 / 62,5020~1 in 3470
Finnish0.014%9 / 64,0120~1 in 3560
African / African American0.0067%5 / 74,9460~1 in 7490
Admixed American · under-sampled0.0017%1 / 59,9920

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position 342 at TM2 start. Neighbors: PHE343 (2.4 Å), PHE341 (2.5 Å — aromatic cluster start), TRP867 (3.6 Å — long-range to TM11 W867!). The W867 contact is structurally significant — TM2-TM11 cross-helix contact.

A342T introduces polarity into TM2 + perturbs TM2-TM11 cross-helix W867 contact. AM 0.13 under-call; multi-phenotype confirms.

Amino-acid chemistry
Alanine (A) → Threonine (T) — small replaced by polar hydroxyl.
Position in the protein
TM2 (residues 340–360) · position 342 near TM2 start (pLDDT 73).

Druggability Assessment

Category 3/4 — Most Druggable (AM under-call). |ΔΔG| 0.72. AlphaMissense 0.13 below threshold but multi-phenotype confirms.

Mechanism: polarity in TM2 + TM2-TM11 W867 cross-helix disruption. Therapeutic: TM2-TM11 interface.

Why this matters

A342T identifies a TM2-TM11 cross-helix contact at W867 — new interface target.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the A342T PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download A342T PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Transmembrane340360 · Helical