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G553S

Category 4 — Stable Fold, Function DisruptedConflictingCytoplasmic · predictedEditorial
GlycineSerine at position 553 · Connecting loop · WFS1 (Wolframin)

Gly→Ser p553 loop AM=0.08 ddg=-0.06 pLDDT=81. ClinVar Conflicting evidence. Atlas mechanism: see structural analysis.

Interactive 3D Structure

Wild-type reference
Wild-type G553 — hydrogen bond to L557
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DynaMut2 mutant · G553S
Mutant S553 — energy-minimized; 1 new contact formed
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Bond changes · DynaMut2 interaction analysis

0 lost1 gained4 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondL556L556Preserved
Hydrogen bondL557L557Preserved
Polar contactL556L556Preserved
Polar contactL557L557Preserved
Van der WaalsL557Gained

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.06kcal/mol
Destabilising — mild
AlphaMissense
0.076
LBen
AlphaFold pLDDT
81
model confidence
Schema
Cat 4
Category 4 — Stable Fold, Function Disrupted
ΔΔG confidence: Standard confidence · Cytoplasmic

This variant is in a water-facing region, which is the regime the stability predictor was built and benchmarked for. Ordinary predictor error still applies.

Clinical Evidence

ClinVar classificationConflicting classifications of pathogenicity
Review statuscriteria provided, conflicting classifications
Associated conditions(no specific conditions catalogued)
InheritanceConflicting ClinVar classifications.
Population frequency (gnomAD v4)Ultra-rare · AF 0.0086%
cDNA changec.1657G>A
ClinVar accessionVCV000215359
Last evaluated2025/10/16 00:00

Observed at very low frequency in gnomAD.

Classified for1★ unverified submission

ClinVar classifies this variant as Conflicting classifications of pathogenicity for Wolfram syndrome (classic) (autosomal recessive, OMIM 222300). Classic Wolfram syndrome is recessive: a single copy does not produce it, and this classification says nothing about a carrier's own risk.

  • Wolfram syndrome (classic)autosomal recessive · OMIM 222300submitted as: Wolfram syndrome 1
  • Submitters conflict on this classification (1★). Treat the conditions above as submitted, not as documented phenotypes.
  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ conflicting classifications. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
AF 0.0086% · 138 / 1,612,396 alleles
Homozygotes
0
Highest-frequency population
Admixed American · AF 0.032%

Highest in Admixed American: AF 0.032% (19 of 60,012 alleles), 3.7x the global figure. The global AF describes the general population, not the at-risk group.

No homozygotes reported in gnomAD v4. For a recessive allele this is expected and is not, on its own, evidence either way.

Ancestry groupAllele freq.AC / ANHom.Carrier est.
Admixed American0.032%19 / 60,0120~1 in 1580
Finnish0.0096%6 / 62,3600~1 in 5200
European (non-Finnish)0.0090%106 / 1,180,0380~1 in 5570
Remaining individuals0.0048%3 / 62,4680~1 in 10410
African / African American0.0040%3 / 74,9400~1 in 12490
South Asian · under-sampled0.0011%1 / 91,0840

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position analysis: THR552 (2.5 Å), LEU554 (2.5 Å — same L554 as R558C neighborhood!), LEU556 (4.4 Å). Same loop as R558C — Ashkenazi flagship region. The Atlas's neighbor extraction surfaces this variant's contacts and connects them to the broader multi-variant target landscape.

Amino-acid chemistry
glycine flexibility lost
Position in the protein
Connecting loop

Druggability Assessment

Cat 3/4 — see structural prose. AlphaMissense below threshold (AM under-call class) but mechanism is structurally identified. Therapeutic strategy: site-directed at contacts identified above, or wet-lab validation if pLDDT borderline/below 50.

Why this matters

Adjacent to R558C Ashkenazi flagship loop.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the G553S PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download G553S PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin