RareResearch.AI
← Back to atlas

G674W

Category 3/4 — Most DruggablePathogenicLumenal · predictedσ-1 candidateEditorial
GlycineTryptophan at position 674 · C-terminal lumenal domain (653-869) · WFS1 (Wolframin)

Glycine → Tryptophan at position 674 in wolframin's C-terminal lumenal domain. ClinVar Pathogenic. AlphaMissense 0.991, DynaMut2 ΔΔG -0.77 kcal/mol (destabilising). The largest substitution at position 674 — backbone flexibility loss combined with massive volume increase.

Interactive 3D Structure

Wild-type reference
Wild-type G674 — hydrogen bond to G670
Fullscreen ↗
DynaMut2 mutant · G674W
Mutant W674 — polar contact contact to W678 lost
Fullscreen ↗

Bond changes · DynaMut2 interaction analysis

0 lost10 gained7 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondG670G670Preserved
Hydrogen bondA677A677Preserved
Hydrogen bondW678W678Preserved
Hydrogen bondK800Gained
Polar contactG670G670Preserved
Polar contactR676R676Preserved
Polar contactA677A677Preserved
Polar contactW678W678Preserved
Aromatic / πW666Gained
Aromatic / πF783Gained
Van der WaalsW666Gained
Van der WaalsG670Gained
Van der WaalsR676Gained
Van der WaalsA677Gained
HydrophobicW666Gained
HydrophobicF783Gained
HydrophobicK800Gained

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.77kcal/mol
Destabilising — mild
AlphaMissense
0.991
LPath
AlphaFold pLDDT
84
model confidence
Schema
Cat 3/4
Category 3/4 — Most Druggable
ΔΔG confidence: Standard confidence · Lumenal

This variant is in a water-facing region, which is the regime the stability predictor was built and benchmarked for. Ordinary predictor error still applies.

Clinical Evidence

ClinVar classificationPathogenic
Review statuscriteria provided, single submitter
Associated conditions(no specific conditions catalogued for G674W — ClinVar Pathogenic by review evidence)
InheritanceInheritance not specified. ClinVar Pathogenic classification establishes clinical relevance.
Population frequency (gnomAD v4)Ultra-rare · AF 0.000068%
cDNA changec.2020G>T
ClinVar accessionVCV003618121
Last evaluated2025/07/23 00:00

Observed at very low frequency in gnomAD.

Classified for1★ unverified submission

ClinVar classifies this variant as Pathogenic, but does not state what it is classified for. ClinVar records the condition only as "not provided". A classification without a phenotype and an inheritance mode cannot be read as a statement about Wolfram syndrome risk or severity.

  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ single submitter. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
AF 0.000068% · 1 / 1,460,802 alleles
Homozygotes
0

Every ancestry group with observed alleles falls below the reporting threshold (min 2 alleles, min 500 sampled) — too sparse to name a highest-frequency population.

No homozygotes reported in gnomAD v4. For a recessive allele this is expected and is not, on its own, evidence either way.

Ancestry groupAllele freq.AC / ANHom.Carrier est.
European (non-Finnish) · under-sampled0.000090%1 / 1,111,9960

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position 674 sits in wolframin's C-terminal lumenal domain, between CYS673 (2.5 Å), PRO675 (2.5 Å), GLY670 (3.1 Å), TRP678 (4.0 Å), and ARG676 (4.5 Å). The TRP678 contact at 4.0 Å is structurally significant: an existing tryptophan four residues downstream in the chain.

Replacing glycine with tryptophan at position 674 has two simultaneous costs. First, the glycine backbone flexibility is gone — the local conformation must rearrange to accommodate any non-glycine residue. Second, the introduced indole ring is roughly an order of magnitude larger than glycine's missing side chain. The local pocket simply does not have space for a tryptophan in the wild-type geometry; substantial local rearrangement is forced.

The combination produces a |ΔΔG| of 0.77 kcal/mol — comparable to G674R's 0.83, both larger than G674E's 0.34. The fold absorbs the substitution, but at meaningful cost. The new W674 plus the existing W678 creates a two-tryptophan cluster in the loop, which might engage in π-stacking with each other in the variant's rearranged geometry — but this is an artifact of the mutation, not a functional feature.

AlphaMissense's 0.991 score confirms severe functional consequence. The pathogenicity mechanism is the same as G674E/G674R: removal of glycine flexibility at a position that requires it, plus secondary disruption from the specific introduced residue's properties.

Amino-acid chemistry
Glycine (G) → Tryptophan (W) — the smallest amino acid replaced by the largest (bulky aromatic indole). Maximum volume contrast in protein chemistry.
Position in the protein
C-terminal lumenal domain · position 674 in the ER lumen (pLDDT 84). Same environment as G674E, G674R.

Druggability Assessment

Category 3/4 — Most Druggable. |ΔΔG| = 0.77 kcal/mol — fold survives. AlphaMissense 0.991 confirms severe functional consequence.

The mechanism combines glycine flexibility loss (shared across the G674E/R/W series) with volume mismatch (specific to G674W). Therapeutic strategy: same backbone-geometry stabilization as G674E and G674R. A drug aimed at the position 674 microregion targets all three known substitutions.

The G674W variant's introduced aromatic ring could be exploited by a drug designed to displace the variant tryptophan back into a wild-type-like geometry — a selective rescue strategy that wouldn't work for G674E or G674R.

Why this matters

G674W completes the three-substitution series at position 674. Together with G674E (charge introduction) and G674R (charge introduction, opposite sign), the series demonstrates that glycine's role at this position is essential and irreplaceable — any non-glycine substitution produces pathogenic consequence through the same fundamental mechanism. The Atlas's per-variant analysis surfaces this convergence; pre-atlas studies of individual variants would not have seen the pattern.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the G674W PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download G674W PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Topological domain653869 · Lumenal
Natural variant674674 · in dbSNP:rs200672755