RareResearch.AI
← Back to atlas

G736R

Category 3/4 — Most DruggablePathogenicLumenal · predictedσ-1 candidateEditorial
GlycineArginine at position 736 · C-terminal lumenal domain (653-869) · WFS1 (Wolframin)

Glycine → Arginine at position 736 in wolframin's C-terminal lumenal domain. ClinVar Pathogenic. AlphaMissense 0.984, DynaMut2 ΔΔG -0.92 kcal/mol (destabilising). Another glycine-removal variant — paralleling the G674 cluster mechanism.

Interactive 3D Structure

Wild-type reference
Wild-type G736 — hydrogen bond to R732
Fullscreen ↗
DynaMut2 mutant · G736R
Mutant R736 — energy-minimized; 9 new contacts formed
Fullscreen ↗

Bond changes · DynaMut2 interaction analysis

0 lost9 gained5 preserved
Interaction typeWild-type partnerMutant partnerStatus
Ionic bondE717Gained
Hydrogen bondE717Gained
Hydrogen bondR732R732Preserved
Polar contactE717Gained
Polar contactR732R732Preserved
Polar contactC765Gained
Polar contactH766H766Preserved
CarbonylR732Gained
CarbonylC733Gained
CarbonylH766H766Preserved
Van der WaalsR732Gained
Van der WaalsH766H766Preserved
HydrophobicR732Gained
HydrophobicI767Gained

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.92kcal/mol
Destabilising — mild
AlphaMissense
0.984
LPath
AlphaFold pLDDT
88
model confidence
Schema
Cat 3/4
Category 3/4 — Most Druggable

Clinical Evidence

ClinVar classificationPathogenic
Review statuscriteria provided, single submitter
Associated conditions(no specific conditions catalogued for G736R — ClinVar Pathogenic by review evidence)
InheritanceInheritance not specified. ClinVar Pathogenic classification with multiple submitters.
Population frequency (gnomAD v4)Ultra-rare · AF 0.00066%
cDNA changec.2206G>C
ClinVar accessionVCV002734647
Last evaluated2022/10/26 00:00

Observed at very low frequency in gnomAD.

Structural Context

Position 736 sits in wolframin's C-terminal lumenal domain. The AlphaFold model places G736 within 5 Å of GLU737 (2.4 Å), TYR735 (2.5 Å), ARG732 (3.1 Å — a four-residue-back contact), HIS766 (3.3 Å — long-range), and ILE767 (4.1 Å). The local environment combines polar (E737, Y735), basic (R732), and titratable (H766) residues with a hydrophobic contact (I767).

The wild-type glycine at 736 plays the same backbone-flexibility role described for the G674 cluster. The neighbor analysis shows particularly tight packing — multiple residues within 4 Å — suggesting the local fold is geometrically constrained, and glycine's lack of side chain is what enables that geometry. Notably, ARG732 sits 3.1 Å away; the wild-type G736 plus R732 form a tight cluster where a single basic residue dominates the local electrostatic character.

Replacing glycine with arginine adds a second positive charge at 3.1 Å from the existing R732. This produces a two-arginine cluster similar to the G674R case — local electrostatic repulsion between adjacent positive charges plus the loss of glycine's backbone flexibility.

The |ΔΔG| of 0.92 reflects this combined cost. AlphaMissense's 0.984 score captures the severe functional consequence — likely disruption of a specific lumenal interaction surface where R732 alone served as the recognized positive charge.

Amino-acid chemistry
Glycine (G) → Arginine (R) — smallest amino acid replaced by a large, positively-charged guanidinium-bearing residue. Same chemistry shift as G674R but at a different position.
Position in the protein
C-terminal lumenal domain · position 736 sits in the ER lumen (pLDDT 88).

Druggability Assessment

Category 3/4 — Most Druggable. |ΔΔG| = 0.92 kcal/mol — fold survives. AlphaMissense 0.984 confirms severe functional consequence.

The mechanism is loss of glycine flexibility plus introduction of a second positive charge adjacent to R732 — disrupting a likely partner-recognition surface where R732 alone was the wild-type signature.

Therapeutic strategy: site-directed small molecules at the R732-G736-Y735 microregion. Pharmacological chaperones biasing the local backbone toward the wild-type glycine-enabled geometry.

Why this matters

G736R parallels the G674R mechanism — glycine removal in a tightly-packed loop adjacent to an existing arginine. The Atlas's per-variant analysis shows that this 'glycine-adjacent-to-arginine' pattern repeats multiple times across the WFS1 lumenal domain, and substitutions at the glycine positions are consistently pathogenic. The class is a coherent therapeutic target — drug discovery against the geometric niche of these glycines.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the G736R PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download G736R PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Topological domain653869 · Lumenal
Natural variant736736 · in WFS1; dbSNP:rs71532864