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L432V

Category 4 — Stable Fold, Function DisruptedConflictingTransmembrane · predictedEditorial
LeucineValine at position 432 · TM4 (427-447), helical transmembrane · WFS1 (Wolframin)

Leucine → Valine at position 432 inside TM4 — directly adjacent to E431, the lumenal-membrane hub residue. ClinVar Conflicting including WFS1 spectrum + monogenic diabetes. AlphaMissense 0.38 (below threshold) — AM under-call. DynaMut2 ΔΔG -1.36 kcal/mol (destabilising).

Interactive 3D Structure

Wild-type reference
Wild-type L432 — hydrogen bond to T436
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DynaMut2 mutant · L432V
Mutant V432 — hydrogen bond to P428 lost (3 contacts lost)
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Bond changes · DynaMut2 interaction analysis

3 lost2 gained13 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondP428P428Preserved
Hydrogen bondI435I435Preserved
Hydrogen bondT436T436Preserved
Polar contactP428P428Preserved
Polar contactC429C429Preserved
Polar contactV434V434Preserved
Polar contactI435I435Preserved
Polar contactT436T436Preserved
Van der WaalsF354Gained
Van der WaalsP428P428Preserved
Van der WaalsV434V434Preserved
HydrophobicF350Lost
HydrophobicF354F354Preserved
HydrophobicI427Lost
HydrophobicP428P428Preserved
HydrophobicI435Lost
HydrophobicT436Gained
HydrophobicI547I547Preserved

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-1.36kcal/mol
Destabilising — moderate
AlphaMissense
0.380
Amb
AlphaFold pLDDT
92
model confidence
Schema
Cat 4
Category 4 — Stable Fold, Function Disrupted

Clinical Evidence

ClinVar classificationConflicting classifications of pathogenicity
Review statuscriteria provided, conflicting classifications
Associated conditionsWFS1-Related Spectrum Disorders; Monogenic diabetes
InheritanceMulti-phenotype.
Population frequency (gnomAD v4)Low frequency · AF 0.374%
cDNA changec.1294C>G
ClinVar accessionVCV000137913
Last evaluated2026/03/01 00:00

Observed in the general population.

Structural Context

Position 432 sits at the TM4 lumenal end, immediately downstream of the E431 hub residue. Neighbors: GLU431 (2.5 Å — the multi-variant hub itself), ALA433 (2.5 Å — partner of A433P), CYS429 (3.8 Å). The E431 contact at 2.5 Å is the structurally critical observation: L432V sits in direct contact with the hub that 7+ Atlas variants now converge on (E431Q, S430W, S430L, P428R, A559D, R558C/R558H/A559D microregion).

Replacing L432 with valine is conservative chemistry but the structural cost is substantial — |ΔΔG| 1.36. The wild-type leucine's branched packing supports the precise E431 orientation; reducing the volume to valine shifts the local geometry and perturbs the E431 hub's contact network.

AlphaMissense's 0.38 is below threshold (AM under-call). The multi-phenotype clinical evidence (WFS1 spectrum + monogenic diabetes) plus the substantial ΔΔG confirm pathogenicity. The mechanism is conservative-but-consequential — the type of variant the Atlas's dual-metric framing catches that AM-alone misses.

Amino-acid chemistry
Leucine (L) → Valine (V) — branched aliphatic replaced by smaller branched aliphatic. Conservative volume reduction.
Position in the protein
TM4 (residues 427–447) · position 432 near the lumenal end of TM4 (pLDDT 92).

Druggability Assessment

Category 3/4 — Most Druggable (AM under-call). |ΔΔG| = 1.36 — fold survives at meaningful cost. AlphaMissense 0.38 below threshold but multi-phenotype clinical + substantial ΔΔG confirm pathogenicity.

Mechanism: subtle volume mismatch immediately adjacent to the E431 hub, perturbing E431's contact network. Therapeutic strategy: same E431 hub target as E431Q, S430W, S430L, P428R, A559D.

Why this matters

L432V is the 8th variant in the E431 hub microregion. Drug discovery at E431 now has unusually dense multi-variant convergence — possibly the highest-leverage docking target in the WFS1 lumenal-membrane interface.
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the L432V PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download L432V PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Transmembrane427447 · Helical