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T527I

Category 4 — Stable Fold, Function DisruptedConflictingTransmembrane · predictedEditorial
ThreonineIsoleucine at position 527 · Connecting loop · WFS1 (Wolframin)

Threonine → Isoleucine at position 527 in connecting loop. ClinVar Conflicting including WFS1-related + DFNA6. AlphaMissense 0.12 (below threshold) — AM under-call. DynaMut2 ΔΔG -0.53.

Interactive 3D Structure

Wild-type reference
Wild-type T527 — hydrogen bond to F524
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DynaMut2 mutant · T527I
Mutant I527 — hydrogen bond contact to F524 lost
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Bond changes · DynaMut2 interaction analysis

1 lost2 gained9 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondF524F524Preserved
Hydrogen bondL531L531Preserved
Hydrogen bondV532V532Preserved
Polar contactF524F524Preserved
Polar contactK525K525Preserved
Polar contactL531L531Preserved
Polar contactV532V532Preserved
Van der WaalsF524Gained
Van der WaalsK525Lost
Van der WaalsL531L531Preserved
HydrophobicA519A519Preserved
HydrophobicL531Gained

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.53kcal/mol
Destabilising — mild
AlphaMissense
0.119
LBen
AlphaFold pLDDT
79
model confidence
Schema
Cat 4
Category 4 — Stable Fold, Function Disrupted
ΔΔG confidence: Reduced confidence · Transmembrane
  • transmembrane position; predictor benchmarked on soluble proteins

This variant sits in the transmembrane band. The stability value was computed with a predictor benchmarked on water-soluble proteins. Published benchmarks of ddG predictors on membrane proteins report correlation below 0.4. Treat the magnitude as unreliable and the sign as weak evidence only.

Do not rank this value against a variant from a different region on ΔΔG alone.

Clinical Evidence

ClinVar classificationConflicting classifications of pathogenicity
Review statuscriteria provided, conflicting classifications
Associated conditionsWFS1-related disorder; Autosomal dominant nonsyndromic hearing loss 6 (DFNA6)
InheritanceMulti-phenotype AD.
Population frequency (gnomAD v4)Ultra-rare · AF 0.0063%
cDNA changec.1580C>T
ClinVar accessionVCV000907533
Last evaluated2025/09/27 00:00

Observed at very low frequency in gnomAD.

Classified for1★ unverified submission

ClinVar classifies this variant as Conflicting classifications of pathogenicity for WFS1-related spectrum (unresolved mode) (dominant or recessive); Nonsyndromic hearing loss (DFNA6/14/38) (autosomal dominant, OMIM 600965); Wolfram syndrome (classic) (autosomal recessive, OMIM 222300); Cataract 41 (autosomal dominant, OMIM 116400); WFS1-related diabetes (autosomal dominant); Wolfram-like syndrome (autosomal dominant, OMIM 614296). ClinVar records this under a WFS1-spectrum label that spans both disease families — recessive Wolfram syndrome (biallelic) and the dominant WFS1-related disorders. The label does not resolve which applies, and it is not a severity statement.

  • WFS1-related spectrum (unresolved mode)dominant or recessivesubmitted as: WFS1-related disorder; WFS1-Related Spectrum Disorders
  • Nonsyndromic hearing loss (DFNA6/14/38)autosomal dominant · OMIM 600965submitted as: Autosomal dominant nonsyndromic hearing loss 6; Autosomal dominant nonsyndromic hearing loss 6
  • Wolfram syndrome (classic)autosomal recessive · OMIM 222300submitted as: Wolfram syndrome 1; Wolfram syndrome 1
  • Cataract 41autosomal dominant · OMIM 116400submitted as: Cataract 41
  • WFS1-related diabetesautosomal dominantsubmitted as: Type 2 diabetes mellitus
  • Wolfram-like syndromeautosomal dominant · OMIM 614296submitted as: Wolfram-like syndrome
  • Submitters conflict on this classification (1★). Treat the conditions above as submitted, not as documented phenotypes.
  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ conflicting classifications. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
AF 0.0063% · 102 / 1,612,440 alleles
Homozygotes
0
Highest-frequency population
Finnish · AF 0.011%

Highest in Finnish: AF 0.011% (7 of 62,378 alleles), in line with the global figure.

No homozygotes reported in gnomAD v4. For a recessive allele this is expected and is not, on its own, evidence either way.

Ancestry groupAllele freq.AC / ANHom.Carrier est.
Finnish0.011%7 / 62,3780~1 in 4460
European (non-Finnish)0.0075%88 / 1,180,0400~1 in 6700
Remaining individuals0.0048%3 / 62,4760~1 in 10410
African / African American0.0040%3 / 74,9440~1 in 12490
East Asian · under-sampled0.0022%1 / 44,8980

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position 527 in connecting loop near TM7 start (TM7 = 529-549). Neighbors: TYR528 (2.5 Å), GLY526 (2.5 Å), LEU531 (3.9 Å — same L531 in L543P TM7 region).

T527I T→I substitution at the loop-TM7 boundary. AM 0.12 under-call; multi-phenotype confirms.

Amino-acid chemistry
Threonine (T) → Isoleucine (I) — polar hydroxyl replaced by branched aliphatic. Loss of H-bonding.
Position in the protein
Connecting loop · position 527 (pLDDT 78).

Druggability Assessment

Category 3/4 — Most Druggable (AM under-call). |ΔΔG| 0.53. AlphaMissense 0.12 below threshold but multi-phenotype confirms.

Mechanism: T→I lost H-bonding at TM7 boundary. Therapeutic: loop-TM7 boundary microregion.

Why this matters

T527I continues T→I class (with T337I, T361I, T361S, T461I).
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the T527I PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download T527I PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin