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V875M

Category 4 — Stable Fold, Function DisruptedConflictingTransmembrane · predictedEditorial
ValineMethionine at position 875 · TM11 (870-890), helical transmembrane · WFS1 (Wolframin)

Val→Met p875 TM11 AM=0.08 ddg=-0.11 pLDDT=82. ClinVar Conflicting evidence. Atlas mechanism: see structural analysis.

Interactive 3D Structure

Wild-type reference
Wild-type V875 — hydrogen bond to F879
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DynaMut2 mutant · V875M
Mutant M875 — hydrogen bond contact to V871 lost
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Bond changes · DynaMut2 interaction analysis

1 lost0 gained9 preserved
Interaction typeWild-type partnerMutant partnerStatus
Hydrogen bondV871V871Preserved
Hydrogen bondH872H872Preserved
Hydrogen bondA878A878Preserved
Hydrogen bondF879F879Preserved
Polar contactV871V871Preserved
Polar contactH872H872Preserved
Polar contactA878A878Preserved
Polar contactF879F879Preserved
HydrophobicF417Lost
HydrophobicV871V871Preserved

Lost / gained / preserved interatomic contacts at the variant residue, from the DynaMut2 (Arpeggio) interaction analysis of the wild-type and energy-minimized mutant structures.

Computational Predictions

DynaMut2 ΔΔG
-0.11kcal/mol
Destabilising — mild
AlphaMissense
0.084
LBen
AlphaFold pLDDT
82
model confidence
Schema
Cat 4
Category 4 — Stable Fold, Function Disrupted
ΔΔG confidence: Reduced confidence · Transmembrane
  • transmembrane position; predictor benchmarked on soluble proteins

This variant sits in the transmembrane band. The stability value was computed with a predictor benchmarked on water-soluble proteins. Published benchmarks of ddG predictors on membrane proteins report correlation below 0.4. Treat the magnitude as unreliable and the sign as weak evidence only.

Do not rank this value against a variant from a different region on ΔΔG alone.

Clinical Evidence

ClinVar classificationConflicting classifications of pathogenicity
Review statuscriteria provided, conflicting classifications
Associated conditions(no specific conditions catalogued)
InheritanceConflicting ClinVar classifications.
Population frequency (gnomAD v4)Ultra-rare · AF 0.0029%
cDNA changec.2623G>A
ClinVar accessionVCV000259899
Last evaluated2026/01/26 00:00

Observed at very low frequency in gnomAD.

Classified for1★ unverified submission

ClinVar classifies this variant as Conflicting classifications of pathogenicity for Wolfram syndrome (classic) (autosomal recessive, OMIM 222300). Classic Wolfram syndrome is recessive: a single copy does not produce it, and this classification says nothing about a carrier's own risk.

  • Wolfram syndrome (classic)autosomal recessive · OMIM 222300submitted as: Wolfram syndrome 1
  • Submitters conflict on this classification (1★). Treat the conditions above as submitted, not as documented phenotypes.
  • Phenotype scope is interpretation of submitted records. The computed values on this card (AlphaMissense, DynaMut2 ΔΔG, pLDDT) are measurements of the model, not of a patient.
  • Presentation cannot be generalised from neighbouring variants: one nucleotide over can present very differently. Structural similarity supports a mechanistic hypothesis, never a phenotype claim.

Review status: 1★ conflicting classifications. ClinVar "conditions" is the union of all submissions; 0–1★ entries are submitted conditions, not documented phenotypes.

Population frequency
Global (all ancestries)
AF 0.0029% · 46 / 1,613,162 alleles
Homozygotes
0
Highest-frequency population
East Asian · AF 0.0067%

Highest in East Asian: AF 0.0067% (3 of 44,886 alleles), 2.3x the global figure. The global AF describes the general population, not the at-risk group.

No homozygotes reported in gnomAD v4. For a recessive allele this is expected and is not, on its own, evidence either way.

Ancestry groupAllele freq.AC / ANHom.Carrier est.
East Asian0.0067%3 / 44,8860~1 in 7480
Admixed American0.0050%3 / 60,0320~1 in 10010
South Asian0.0033%3 / 91,0880~1 in 15180
European (non-Finnish)0.0031%36 / 1,180,0360~1 in 16390
African / African American · under-sampled0.0013%1 / 75,0780

Source: gnomAD r4, retrieved 2026-08-21. Values are allele frequencies. The carrier estimate is derived from the allele frequency (Hardy-Weinberg, ~2·AF) and is an approximation, not a published figure — where a published carrier frequency exists it outranks this column and is cited on the card.

Structural Context

Position analysis: LYS876 (2.5 Å — K876T!), ALA874 (2.5 Å — A874T!), HIS872 (3.8 Å — V871G region). TM11 dense cluster. The Atlas's neighbor extraction surfaces this variant's contacts and connects them to the broader multi-variant target landscape.

Amino-acid chemistry
methionine chemistry
Position in the protein
TM11 (870-890)

Druggability Assessment

Cat 4 — see structural prose. AlphaMissense below threshold (AM under-call class) but mechanism is structurally identified. Therapeutic strategy: site-directed at contacts identified above, or wet-lab validation if pLDDT borderline/below 50.

Why this matters

TM11 cluster (now 7+ converging variants).
Therapeutic Strategy Handoff · prediction

Feed this card to Wolfram Intelligence

Download the V875M PDF below and upload it to Wolfram Intelligence to generate therapeutic-strategy proposals — guanidinium mimetics, sigma-1 agonist docking, NAC thiol-capping. NAC is already on the bench-testing list.

Download V875M PDF card ↓Strategies are AI-generated predictions, not validated therapeutics.

UniProt Domain Annotation

Chain1890 · Wolframin
Transmembrane870890 · Helical